An adult case of Bland-White-Garland syndrome with collaterals from the bronchial artery.
We report herein an adult case of anomalous origin of the left coronary artery from the pulmonary artery (Bland-White-Garland syndrome; BWG syndrome). The patient had chest discomfort during exercise and signs of mitral regurgitation. We diagnosed him as having BWG syndrome by angiography, and performed surgical treatment. At the operation, retrograde coronary blood flow was found through the left coronary artery during aortic cross-clamping. This suggested extracardiac anastomosis from peripheral arteries to the left coronary artery. Since the collateral blood flow was considerable during aortic cross-clamping, only the left coronary artery was closed. A collateral from the left bronchial artery to the left circumflex artery was demonstrated by postoperative angiography. Cases of adults with BWG syndrome are rare, and this may be the first report of a collateral from the bronchial artery.
Ishihata
T
T
Department of Cardiology and Cardiovascular Surgery, Ohta Nishinouchi Hospital, Fukushima, Japan.
Takeda
H
H
Katohno
E
E
Techigawara
M
M
Owada
K
K
Murata
N
N
Ohta
H
H
Maruyama
Y
Y
D000328:Adult; D017130:Angioplasty / Q000379:methods; D001981:Bronchial Arteries / Q000002:abnormalities*; D006328:Cardiac Catheterization; D017023:Coronary Angiography; D003330:Coronary Vessel Anomalies / Q000175:diagnosis* / Q000503:physiopathology / Q000601:surgery*; D005080:Exercise Test; D006439:Hemodynamics; D006801:Humans; D008297:Male; D017202:Myocardial Ischemia / Q000209:etiology; D013577:Syndrome