title: Cystic rectal duplication: a rare cause of neonatal intestinal obstruction.
abstract: A case of cystic rectal duplication revealed on day 2 of life by a low intestinal occluding syndrome is reported. Radiologic imaging (ultrasonography, cystography, rectography) showed a large, retrorectal liquid formation in the pelvis and abdomen, with pelvic compression of the terminal alimentary canal and lower urinary tract. Magnetic resonance imaging demonstrated a liquid formation with clearly defined edges and no medullary involvement, thus ruling out the possibility of a previous meningeal hernia. Biological markers were within normal limits. On day 4, a 9 x 6-cm cystic rectal duplication was removed, followed by a temporary colostomy. Pathologic examination demonstrated typical rectal architecture with ciliated cells. Radiologic and clinical findings at 2-month follow-up were reassuring. This case report is exceptional for the following reasons: (1) As a rule, rectal duplications are relatively rare (70 cases reported in the literature); (2) The means of disclosing a neonatal rectal duplication is unusual (4 cases reported in the literature); (3) The volume of the malformation was considerable; and (4) Heterotopic ciliated epithelium was present.
authors.affiliation: Department of Pediatric Surgery, Centre Hospitalier de Besançon, Hôpital Saint-Jacques, 2, place Saint-Jacques, 25030 Besançon Cedex, France.
authors.forename: A
authors.initials: A
authors.lastname: Mboyo
authors.forename: O
authors.initials: O
authors.lastname: Monek
authors.forename: R
authors.initials: R
authors.lastname: Massicot
authors.forename: L
authors.initials: L
authors.lastname: Martin
authors.forename: O
authors.initials: O
authors.lastname: Destuynder
authors.forename: A
authors.initials: A
authors.lastname: Lemouel
authors.forename: D
authors.initials: D
authors.lastname: Aubert
mesh_terms: D003560:Cysts / Q000150:complications* / Q000601:surgery; D006801:Humans; D007231:Infant, Newborn; D007410:Intestinal Diseases / Q000150:complications* / Q000601:surgery; D007415:Intestinal Obstruction / Q000209:etiology* / Q000601:surgery; D008297:Male; D012007:Rectum / Q000002:abnormalities* / Q000601:surgery