Monocanalicular intubation for dacryostenosis in oculo-auriculo-vertebral dysplasia (hemifacial microsomia) with congenital corneal anesthesia.
OBJECTIVE
To present a case of oculo-auriculo-vertebral dysplasia associated with corneal anesthesia and ipsilateral dacryostenosis that was successfully treated with monocanalicular lacrimal intubation.


METHODS
Case report.


RESULTS
Previous neurotrophic corneal ulcers in a child with hemifacial microsomia had become secondarily infected from a stagnant tear lake, resulting in significant corneal scarring and visual loss. A single monocanalicular stent maintained nasolacrimal patency without causing further corneal trauma, despite constant medial gaze because of wide lateral tarsorrhaphy and contralateral occlusion therapy for amblyopia.


CONCLUSIONS
Monocanalicular stents may aid the treatment of dacryostenosis in the face of compromised corneal sensation.
Mazzoli
R A
RA
Department of Ophthalmology, Madigan Army Medical Center, Tacoma, Washington 98431, USA.
Raymond
W R
WR
Ainbinder
D J
DJ
Hansen
E A
EA
Parmley
V C
VC
Skidmore
E C
EC
D000015:Abnormalities, Multiple; D002675:Child, Preschool; D003315:Cornea / Q000294:innervation; D003316:Corneal Diseases / Q000151:congenital*; D005146:Facial Asymmetry / Q000151:congenital*; D005260:Female; D006801:Humans; D006987:Hypesthesia / Q000151:congenital*; D007440:Intubation; D007767:Lacrimal Duct Obstruction / Q000151:congenital / Q000628:therapy*; D009301:Nasolacrimal Duct / Q000002:abnormalities