Haemopneumothorax from congenital cystic adenomatoid malformation in a cryptorchidism patient.
Congenital cystic adenomatoid malformation (CCAM) of the lung is an uncommon congenital anomaly, especially in young adults. This study reports an 18-yr-old male with CCAM involving the right upper lobe, who presented with a moderate spontaneous haemopneumothorax initially. The patient also had bilateral abdominal cryptorchidism which required surgical treatment earlier in childhood. The chest radiographs and contrast-enhanced computed tomographic scan of the chest showed a multicystic lesion with air-fluid levels in the right upper lung. The right upper lobe was resected through a posterolateral thoracotomy. Histological examination confirmed the diagnosis of CCAM. To the authors' knowledge, congenital cystic adenomatoid malformation presenting with spontaneous haemopneumothorax and haemoptysis has never been described in the literature.
Lee
S C
SC
Dept of Surgery, Tri-Service General Hospital, National Defense Medical Center, Taipei, Taiwan.
Cheng
Y L
YL
Yu
C P
CP
D000328:Adult; D003456:Cryptorchidism / Q000150:complications*; D015615:Cystic Adenomatoid Malformation of Lung, Congenital / Q000150:complications* / Q000000981:diagnostic imaging / Q000601:surgery; D006468:Hemopneumothorax / Q000000981:diagnostic imaging / Q000209:etiology*; D006801:Humans; D008297:Male; D011859:Radiography