title: Cardiac imaging in a patient with anomalous origin of the left coronary artery from the pulmonary artery--a case report.
abstract: Anomalous origin of the left coronary artery from the pulmonary artery (ALCAPA) is an uncommon congenital heart disease and has a high mortality rate in infancy. However, myocardial ischemia does not develop until adolescence or adulthood in about 10% of patients. Moreover, the diagnosis of ALCAPA is often difficult in cases without heart murmur or cardiac symptoms. The authors report the case of a 31-year-old man with ALCAPA. He was admitted to the hospital for evaluation of mild shortness of breath at exercise, but he had no typical chest symptoms due to myocardial ischemia or heart failure until age 31 and he had no heart murmur. Moreover, electrocardiogram did not show an old myocardial infarction or myocardial ischemia. Therefore, the authors did not suspect ALCAPA until they performed transthoracic echocardiography and exercise-stress single photon emission computed tomography (SPECT) with Tc-99m-tetrofosmin. The final diagnosis was established from the results of coronary arteriography. In the present case, a transthoracic echocardiogram showed abnormal coronary circulation, and exercise-stress SPECT revealed reversible myocardial ischemia. Transthoracic echocardiography and myocardial SPECT imaging could be a useful noninvasive tools for diagnosing the ALCAPA.
authors.affiliation: Department of Cardiology, Hakodate Goryokaku Hospital, Japan.
authors.forename: R
authors.initials: R
authors.lastname: Noda
authors.forename: H
authors.initials: H
authors.lastname: Sasao
authors.forename: M
authors.initials: M
authors.lastname: Kyuma
authors.forename: Y
authors.initials: Y
authors.lastname: Ichikawa
authors.forename: T
authors.initials: T
authors.lastname: Hasegawa
authors.forename: A
authors.initials: A
authors.lastname: Endo
authors.forename: H
authors.initials: H
authors.lastname: Oimatsu
authors.forename: T
authors.initials: T
authors.lastname: Takada
mesh_terms: D000328:Adult; D003330:Coronary Vessel Anomalies / Q000000981:diagnostic imaging*; D017548:Echocardiography, Transesophageal / Q000379:methods*; D004562:Electrocardiography; D005080:Exercise Test; D006801:Humans; D008297:Male; D011651:Pulmonary Artery / Q000002:abnormalities*; D012680:Sensitivity and Specificity; D015899:Tomography, Emission-Computed, Single-Photon / Q000379:methods*