title: [A case of racemose hemangioma of a bronchial artery complicated with atrial septal defect and localized peripheral ground-glass opacity].
abstract: We report a case of racemose hemangioma of the right bronchial artery complicated with an atrial septal defect (ASD) and ground-glass opacity localized in the right upper lung lobe. A 42-year-old woman was admitted for the pre-operative assessment of ASD. Aortography and selective angiography revealed that the right bronchial artery was markedly dilated and convoluted, draining into the right intercostal arteries and the right upper pulmonary vein. The patient was suffering from exertional dyspnea, but produced no bloody sputum. Since videobronchoscopy showed normal mucosal findings without bronchiectasis, primary racemose hemangioma of the right bronchial artery was diagnosed, and was treated by ligation of the bronchial artery and patch-closure of the ASD. The ground-glass opacity observed preoperatively in the periphery of the right upper lung lobe vanished after surgery. This opacity was considered to have been localized pulmonary congestion due to augmented hydrostatic pressure in the right upper pulmonary vein, induced by increased pulmonary blood flow through the ASD and the drainage route of the racemose bronchial artery into right upper pulmonary vein.
authors.affiliation: Second Department of Internal Medicine, Gunma University School of Medicine, Maebashi, Japan.
authors.forename: Satoko
authors.initials: S
authors.lastname: Akaishi
authors.forename: Tatsuo
authors.initials: T
authors.lastname: Suga
authors.forename: Satoko
authors.initials: S
authors.lastname: Kakegawa
authors.forename: Yoichi
authors.initials: Y
authors.lastname: Hoshino
authors.forename: Junichi
authors.initials: J
authors.lastname: Nakagawa
authors.forename: Nozomi
authors.initials: N
authors.lastname: Aoki
authors.forename: Mahito
authors.initials: M
authors.lastname: Sato
authors.forename: Toshitaka
authors.initials: T
authors.lastname: Maeno
authors.forename: Yoshichika
authors.initials: Y
authors.lastname: Sando
authors.forename: Akira
authors.initials: A
authors.lastname: Hasegawa
authors.forename: Masahiko
authors.initials: M
authors.lastname: Kurabayashi
mesh_terms: D000328:Adult; D001981:Bronchial Arteries / Q000002:abnormalities* / Q000000981:diagnostic imaging; D005260:Female; D006344:Heart Septal Defects, Atrial / Q000150:complications*; D006391:Hemangioma / Q000000981:diagnostic imaging / Q000209:etiology*; D006801:Humans; D008168:Lung / Q000000981:diagnostic imaging*; D011859:Radiography; D019043:Vascular Neoplasms / Q000000981:diagnostic imaging / Q000209:etiology*