title: Hemobilia in hereditary hemorrhagic telangiectasia: an unusual complication of endoscopic retrograde cholangiopancreatography.
abstract: Hepatobiliary manifestations of hereditary hemorrhagic telangiectasia (HHT) are rare, but often involve cholestasis. We report here a case of HHT associated with cholestasis due to common bile duct stenosis. Attempted balloon dilation of the stenosis during endoscopic retrograde cholangiopancreatography (ERCP) resulted in hemobilia. Hemostasis was achieved by adjusting the nasobiliary drain. The aim of this report is to highlight the biliary manifestations of HHT and draw attention to an unusual complication of ERCP in this setting.
authors.affiliation: Gastrenterology and Hepatology Intensive Care Unit, Dept. of Medicine II, Santa Maria Hospital, Av. Prof. Egas Moniz, 1649-035 Lisbon, Portugal. tcostamacedo@clix.pt
authors.forename: T
authors.initials: T
authors.lastname: Costa Macedo
authors.forename: R
authors.initials: R
authors.lastname: Maldonado
authors.forename: A
authors.initials: A
authors.lastname: Valente
authors.forename: R
authors.initials: R
authors.lastname: Palma
authors.forename: M
authors.initials: M
authors.lastname: Raimundo
authors.forename: M
authors.initials: M
authors.lastname: Liberato
authors.forename: I
authors.initials: I
authors.lastname: Távora
authors.forename: P
authors.initials: P
authors.lastname: Alexandrino
authors.forename: M
authors.initials: M
authors.lastname: Carneiro de Moura
mesh_terms: D002404:Catheterization / Q000379:methods; D002760:Cholangiopancreatography, Endoscopic Retrograde / Q000009:adverse effects / Q000379:methods; D004322:Drainage / Q000379:methods; D006431:Hemobilia / Q000209:etiology* / Q000628:therapy; D006801:Humans; D008297:Male; D008875:Middle Aged; D013683:Telangiectasia, Hereditary Hemorrhagic / Q000150:complications*