Life-threatening respiratory failure due to cranial dystonia after dental procedure in a patient with multiple system atrophy.
We report on a woman with a an 8-year history of multiple system atrophy with predominance of parkinsonism who developed jaw-locking oromandibular dystonia within hours after insertion of ill-fitting dentures. Dystonia spread rapidly to involve other facial muscles and the larynx causing stridor with respiratory failure necessitating crush intubation.
Hamzei
Farsin
F
Neurology Department, Hamburg University, Hamburg, Germany.
Rijntjes
Michel
M
Gbadamosi
Joystone
J
Fuchs
Kornelius
K
Weiller
Cornelius
C
Münchau
Alexander
A
D001921:Brain / Q000473:pathology; D003778:Dentures / Q000009:adverse effects*; D004421:Dystonia / Q000209:etiology* / Q000503:physiopathology*; D005260:Female; D006801:Humans; D008279:Magnetic Resonance Imaging; D008334:Mandible / Q000503:physiopathology*; D008875:Middle Aged; D019578:Multiple System Atrophy / Q000473:pathology; D012131:Respiratory Insufficiency / Q000209:etiology*; D014081:Tooth Extraction / Q000379:methods*