Anorectal agenesis with a rectourethral fistula diagnosed in an adult: report of a case.
We report an unusual case of anorectal agenesis with a rectourethral fistula diagnosed in a 48-year-old man. The patient presented after noticing hematuria, although he had been aware of urinary leakage from his colostomy with occasional fecal urine for about 4 years. He had had a double-barrel colostomy created soon after birth for an imperforate anus, with revision at the age of 4 years to correct a prolapse of the stoma, but his malformation had never been repaired. We performed a physical examination, which did not reveal a perineal fistula, but urethrocystography demonstrated high anorectal agenesis with a rectourethral fistula. Thus, we resected the rectourethral fistula and created an end-colostomy. The patient had an uneventful postoperative course, and was discharged in good health on postoperative day 19. To our knowledge, this is the oldest patient to be diagnosed with anorectal agenesis and undergo resection of a rectourethral fistula.
Odaka
Akio
A
Department of Surgery, Saitama Medical Center, Saitama Medical School, 1981 Tsujido, Kamoda, Kawagoe, , Saitama 350-8550, Japan.
Takahashi
Shigeki
S
Tanimizu
Takemaru
T
Kawashima
Hiroshi
H
Okada
Norimichi
N
Inokuma
Shigehisa
S
Yamada
Hirofumi
H
Ishida
Hideyuki
H
Hoshino
Takanobu
T
Satomi
Akira
A
Hashimoto
Daijo
D
D001006:Anus, Imperforate / Q000150:complications* / Q000601:surgery; D006801:Humans; D008297:Male; D008875:Middle Aged; D012003:Rectal Fistula / Q000175:diagnosis* / Q000601:surgery; D014522:Urethral Diseases / Q000175:diagnosis* / Q000601:surgery; D014548:Urinary Fistula / Q000175:diagnosis* / Q000601:surgery