title: SAPHO syndrome with temporomandibular joint ankylosis: clinical, radiological, histopathological, and therapeutical correlations.
abstract: The SAPHO syndrome is characterized by specific clinical manifestations of synovitis, acne pustulosis, hyperostosis, and osteitis. It is a rare disease with a combination of osseous and articular manifestations associated with skin lesions. We describe a patient with SAPHO syndrome of the mandible and involvement of the temporomandibular joint (TMJ ankylosis). The findings from orthopantomography, computed tomography (CT), and clinical and histopathological examinations are compared and analyzed to improve the final diagnosis. Our patient was submitted to a bilateral high condylectomy and coronoidectomy to correct the open mouth limitation. No previous report of SAPHO syndrome associated with secondary TMJ ankylosis was found in the literature.
authors.affiliation: Department of Stomatology, School of Dentistry, University of São Paulo, São Paulo, Brazil.
authors.forename: Estevam Rubens
authors.initials: ER
authors.lastname: Utumi
authors.forename: Marcelo Augusto
authors.initials: MA
authors.lastname: Oliveira Sales
authors.forename: Elio Hitoshi
authors.initials: EH
authors.lastname: Shinohara
authors.forename: André
authors.initials: A
authors.lastname: Takahashi
authors.forename: Fábio Luiz
authors.initials: FL
authors.lastname: Coracin
authors.forename: Rodney Garcia
authors.initials: RG
authors.lastname: Rocha
authors.forename: Marcelo Gusmão
authors.initials: MG
authors.lastname: Paraíso Cavalcanti
mesh_terms: D020083:Acquired Hyperostosis Syndrome / Q000150:complications* / Q000000981:diagnostic imaging; D000328:Adult; D000844:Ankylosis / Q000150:complications* / Q000000981:diagnostic imaging; D006801:Humans; D008297:Male; D011862:Radiography, Panoramic; D016059:Range of Motion, Articular; D013705:Temporomandibular Joint Disorders / Q000150:complications* / Q000000981:diagnostic imaging