SAPHO syndrome with temporomandibular joint ankylosis: clinical, radiological, histopathological, and therapeutical correlations.
The SAPHO syndrome is characterized by specific clinical manifestations of synovitis, acne pustulosis, hyperostosis, and osteitis. It is a rare disease with a combination of osseous and articular manifestations associated with skin lesions. We describe a patient with SAPHO syndrome of the mandible and involvement of the temporomandibular joint (TMJ ankylosis). The findings from orthopantomography, computed tomography (CT), and clinical and histopathological examinations are compared and analyzed to improve the final diagnosis. Our patient was submitted to a bilateral high condylectomy and coronoidectomy to correct the open mouth limitation. No previous report of SAPHO syndrome associated with secondary TMJ ankylosis was found in the literature.
Utumi
Estevam Rubens
ER
Department of Stomatology, School of Dentistry, University of São Paulo, São Paulo, Brazil.
Oliveira Sales
Marcelo Augusto
MA
Shinohara
Elio Hitoshi
EH
Takahashi
André
A
Coracin
Fábio Luiz
FL
Rocha
Rodney Garcia
RG
Paraíso Cavalcanti
Marcelo Gusmão
MG
D020083:Acquired Hyperostosis Syndrome / Q000150:complications* / Q000000981:diagnostic imaging; D000328:Adult; D000844:Ankylosis / Q000150:complications* / Q000000981:diagnostic imaging; D006801:Humans; D008297:Male; D011862:Radiography, Panoramic; D016059:Range of Motion, Articular; D013705:Temporomandibular Joint Disorders / Q000150:complications* / Q000000981:diagnostic imaging