[Chorioangiomatosis: a rare etiology of nonimmune hydrops fetalis. Obstetric and pediatric implications for patient care].
We report a case of chorioangiomatosis with hydrops fetalis as a complication.


METHODS
Hydrops fetalis associated with fetal distress led to preterm birth at 33 GW. Resuscitation was needed at birth. A systematic histologic exam showed diffuse chorioangiomatosis. There was no congenital hemangioma.


CONCLUSIONS
We describe the features of chorioangiomatosis, a rare cause of nonimmune hydrops fetalis. Prenatal diagnosis of chorioangiomatosis before early recognition of severe maternal and fetal complications during pregnancy is infrequent, thus precluding early management of the pregnancy. Reports of associated chorioangioma and infantile hemangioma are frequent, illustrated with a recent pathophysiological hypothesis involving embolism of a placental angioblast as for the cause of congenital hemangioma. Investigations for associated cutaneous or visceral infantile hemangioma should be undertaken when chorioangioma is diagnosed.
Baruteau
J
J
Service d'hépato-gastroentérologie pédiatrique, hôpital des Enfants, 330 avenue de Grande-Bretagne, Toulouse cedex 09, France.
Joomye
R
R
Muller
J-B
JB
Vinceslas
C
C
Baraton
L
L
Joubert
M
M
Paumier
A
A
Roze
J-C
JC
D000328:Adult; D005260:Female; D006801:Humans; D015160:Hydrops Fetalis / Q000209:etiology* / Q000628:therapy; D007231:Infant, Newborn; D010920:Placenta / Q000098:blood supply*; D011247:Pregnancy; D054079:Vascular Malformations