title: Recurrent submandibular gland swelling as a first manifestation in a child with primary Sjögren syndrome.
abstract: We reported 1 case of primary Sjögren syndrome in a child. The patient complained recurrent submandibular inflammation for more than 2 years without apparent sicca presentations, and Schirmer test resulted negative. However, ultrasound showed hypoechoic areas in the gland, laboratory tests reported the positivity of Sjögren's syndrome A antigen and Sjögren's syndrome B antigen, and biopsy presented periductal lymphocytic infiltration. Therefore, a diagnosis of primary Sjögren syndrome was conducted. Treatment of it required a multidisciplinary team.
authors.affiliation: Department of Oromaxillofacial-Head and Neck Surgery, Department of Oral and Maxillofacial Surgery, School of Stomatology, China Medical University, Shenyang, Liaoning, PR China.
authors.forename: Qi-Gen
authors.initials: QG
authors.lastname: Fang
authors.forename: Fa-Yu
authors.initials: FY
authors.lastname: Liu
authors.forename: Chang-Fu
authors.initials: CF
authors.lastname: Sun
mesh_terms: D001706:Biopsy; D002648:Child; D003937:Diagnosis, Differential; D004487:Edema / Q000473:pathology*; D005260:Female; D006801:Humans; D012008:Recurrence; D012859:Sjogren's Syndrome / Q000175:diagnosis*; D013363:Submandibular Gland / Q000473:pathology*