title: Currarino syndrome in an adult presenting with a presacral abscess: a case report.
abstract: BACKGROUND
  Currarino syndrome (Currarino triad) was described in 1981 as a triad syndrome with a common embryogenesis in infants and with three characteristics: anorectal stenosis, a defect in the sacral bone, and a presacral mass. We describe here an unusual case of Currarino syndrome in an adult presenting with a presacral abscess but no meningitis.
  
  
  METHODS
  A 32-year-old Japanese man presented with fever, arthralgia and buttock pain. A digital rectal examination showed mild rectal stenosis with local warmth and tenderness in the posterior wall of his rectum. Computed tomography showed a scimitar-shaped deformity of his sacrum and an 8cm presacral mass, which continued to a pedicle of his deformed sacrum. This was diagnosed as Currarino syndrome with a presacral abscess. The abscess was drained by a perianal approach with our patient treated with antibiotics. His symptoms soon disappeared. After three months, an excision was performed through a posterior sagittal approach. His postoperative course was uneventful and he was discharged 10 days after surgery. A histopathological examination revealed an infected epidermoid cyst. He has been free from recurrence as of four years and six months after surgery.
  
  
  CONCLUSIONS
  We report a case of Currarino syndrome in an adult who presented with a presacral abscess but no meningitis. Abscess drainage followed by radical surgery resulted in a successful outcome.
authors.affiliation: Department of Gastroenterological Surgery, Division of Cancer Medicine, Graduate School of Medical Science, Kanazawa University, 13-1 Takara-machi, Kanazawa, Ishikawa 920-8641, Japan. pignite@me.com.
authors.forename: Masatoshi
authors.initials: M
authors.lastname: Shoji
authors.forename: Naomi
authors.initials: N
authors.lastname: Nojima
authors.forename: Akemi
authors.initials: A
authors.lastname: Yoshikawa
authors.forename: Wataru
authors.initials: W
authors.lastname: Fukushima
authors.forename: Naotaka
authors.initials: N
authors.lastname: Kadoya
authors.forename: Hisashi
authors.initials: H
authors.lastname: Hirosawa
authors.forename: Ryohei
authors.initials: R
authors.lastname: Izumi