title: Chronic intestinal pseudo-obstruction due to lymphocytic intestinal leiomyositis: Case report and literature review.
abstract: Lymphocytic intestinal leiomyositis is a rare entity, which causes chronic intestinal pseudo-obstruction (CIPO) in children. We present the first case of a boy who had pure red cell anemia 1 year before onset. Prolonged ileus developed after gastroenteritis and the patient was diagnosed using a biopsy of the intestinal wall. Findings from the present case indicate that there are three important factors for accurate diagnosis: history of enteritis, positive serum smooth muscle antibody, and lymphocyte infiltration with muscle destruction in the muscularis propria in the intestinal wall. Earlier diagnosis and induction of immunosuppressive therapy may be essential for a better outcome.
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Keiichi
authors.initials: K
authors.lastname: Uchida
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Kohei
authors.initials: K
authors.lastname: Otake
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Mikihiro
authors.initials: M
authors.lastname: Inoue
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Yuhki
authors.initials: Y
authors.lastname: Koike
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Kohei
authors.initials: K
authors.lastname: Matsushita
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Toshimitsu
authors.initials: T
authors.lastname: Araki
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Yoshiki
authors.initials: Y
authors.lastname: Okita
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Koji
authors.initials: K
authors.lastname: Tanaka
authors.affiliation: Department of Pathology, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Katsunori
authors.initials: K
authors.lastname: Uchida
authors.affiliation: Department of Pediatrics, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Noriko
authors.initials: N
authors.lastname: Yodoya
authors.affiliation: Department of Pediatrics, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Shotaro
authors.initials: S
authors.lastname: Iwamoto
authors.affiliation: Division of Gastroenterology, Department of Medical Specialties, National Center for Child Health and Development, Tokyo, Japan.
authors.forename: Katsuhiro
authors.initials: K
authors.lastname: Arai
authors.affiliation: Department of Gastrointestinal and Pediatric Surgery, Mie University Graduate School of Medicine, Tsu, Mie, Japan;
authors.forename: Masato
authors.initials: M
authors.lastname: Kusunoki
keywords: Chronic intestinal pseudo-obstruction (CIPO); intestine; leiomyositis; pseudo-obstruction