title: Bronchial-pulmonary arterial fistula with primary racemose hemangioma.
abstract: Bronchial-pulmonary arterial fistula (BPAF) is a rare vascular malformation complicated with racemose hemangioma. We report a case of a 65-year-old male with BPAF with primary racemose hemangioma. Bronchial arteriography demonstrated convolution, dilation, and aneurysm connected with pulmonary artery, suggesting the presence of BPAF, in the left upper lobe. Since a 20-mm sized aneurysm of bronchial artery and BPAF coexisted, he underwent ligation of bronchial arterial aneurysm and left upper lobectomy to prevent hemoptysis. As neither history of prior illness nor histopathologic findings of vascular inflammation was seen, the present case demonstrated BPAF with primary racemose hemangioma. Establishment of non-invasive treatment strategy for BPAF is urgently required.
authors.affiliation: Department of Respiratory Medicine Juntendo University Graduate School of Medicine Tokyo Japan.
authors.forename: Miharu
authors.initials: M
authors.lastname: Kato
authors.affiliation: Department of Respiratory Medicine Juntendo University Graduate School of Medicine Tokyo Japan.
authors.forename: Yoshiteru
authors.initials: Y
authors.lastname: Morio
authors.affiliation: Department of General Thoracic Surgery Juntendo University Graduate School of Medicine Tokyo Japan.
authors.forename: Takeshi
authors.initials: T
authors.lastname: Matsunaga
authors.affiliation: Department of Radiology Juntendo University Graduate School of Medicine Tokyo Japan.
authors.forename: Akihiko
authors.initials: A
authors.lastname: Shiraishi
authors.affiliation: Department of Diagnostic Pathology, Japan Labour Health and Welfare Organization Kanto Rosai Hospital Kanagawa Japan.
authors.forename: Toshimasa
authors.initials: T
authors.lastname: Uekusa
authors.affiliation: Department of Respiratory Medicine Juntendo University Graduate School of Medicine Tokyo Japan.
authors.forename: Kazuhisa
authors.initials: K
authors.lastname: Takahashi
keywords: Bronchial‐pulmonary arterial fistula; pulmonary vascular malformation; racemose hemangioma