Congenital anterior urethrocutaneous fistula: 3 new cases and review of literature.
OBJECTIVE
Congenital anterior urethrocutaneous fistula, is a rare anomaly characterised by fistulisation of penile urethra to skin and presence of a concomitant normal or hypospadiac external urethral meatus. It may be seen as an isolated anomaly or may accompany genitourinary or anorectal malformations. We aim to present 3 new cases and define the common properties of patients stated in literature.


METHODS
Information of 3 patients aged 2, 3 and 6 with this diagnosis were reviewed retrospectively and features of 51 patients in 25 articles with literature search.


RESULTS
From the patients we operated, 2 had midpenile and 1 had subcoronal fistula. Urethral meatus was at tip of glans in all with 1 stenotic meatus. Two-layered primary repair was performed in 3 patients and deep ventral incision on urethral plate with meatotomy were added to fistula repair in one with stenotic meatus. Fistula recurred in this patient but resolved spontaneously after dilatations. In literature, most common fistula site was subcoronal in 27 (52.9%). Hypospadias was in 11.8% and associated genitourinary anomaly was detected in 21.5% of patients. Fistula recurrence ratio was 7.8% using different surgical techniques.


CONCLUSIONS
Congenital anterior urethrocutaneous fistula is frequently located in subcoronal level and usually a normal urethra distal to it. Physical examination is important to detect additional anomalies. Success rates are high with primary repair techniques.
Department of Pediatric Surgery. Gaziantep University Faculty of Medicine. Gaziantep. Turkey.
Idil Rana
IR
User
Department of Pediatric Surgery. Gaziantep University Faculty of Medicine. Gaziantep. Turkey.
Süleyman Cüneyt
SC
Karakus
Department of Pediatric Surgery. Gaziantep University Faculty of Medicine. Gaziantep. Turkey.
Vedat
V
Akçaer
Department of Pediatric Surgery. Gaziantep University Faculty of Medicine. Gaziantep. Turkey.
Bülent Hayri
BH
Özokutan
Department of Pediatric Surgery. Gaziantep University Faculty of Medicine. Gaziantep. Turkey.
Haluk
H
Ceylan
D002648:Child; D002675:Child, Preschool; D017577:Cutaneous Fistula / Q000151:congenital* / Q000175:diagnosis / Q000601:surgery; D006801:Humans; D008297:Male; D014522:Urethral Diseases / Q000151:congenital* / Q000175:diagnosis / Q000601:surgery; D014548:Urinary Fistula / Q000151:congenital* / Q000175:diagnosis / Q000601:surgery