Orbital infarction syndrome after multiple percutaneous sclerotherapy sessions for facial low-flow vascular malformation: A case report and literature review.
Vision loss following sclerotherapy for facial vascular malformations (VMs) is a rare but detrimental complication. Here, we report a case of an 11-year-old boy with acute onset blepharoptosis, ophthalmoplegia, and blindness in his right eye after the 14 th sclerotherapy session (percutaneous intralesional injection of sodium tetradecyl sulfate) for a right facial low-flow VM without orbital involvement. Computed tomography angiography revealed no contrast enhancement in the right ophthalmic artery, superior ophthalmic vein, or extraocular muscles. He presented with the hallmarks of orbital infarction syndrome: Clear signs of anterior and posterior segment ischemia and disrupted arterial flow to the extraocular muscles. His blepharoptosis and eye movement improved 4 months later; however, he remained blind, and phthisis bulbi developed eventually. Thus, sclerotherapy for facial VM-even without orbital involvement--may result in severe ocular and orbital complications.
Department of Ophthalmology, Cathay General Hospital, Taipei, Taiwan.
Weng Sut
WS
Sio
Department of Ophthalmology, Cathay General Hospital, Taipei, Taiwan.
Shwu-Huey
SH
Lee
Department of Ophthalmology, Cathay General Hospital, Taipei, Taiwan.
I-Chia
IC
Liang
D001763:Blepharoptosis / Q000175:diagnosis / Q000209:etiology; D001766:Blindness / Q000175:diagnosis / Q000209:etiology; D002648:Child; D000072226:Computed Tomography Angiography; D005145:Face / Q000098:blood supply*; D006801:Humans; D007238:Infarction / Q000175:diagnosis / Q000209:etiology*; D008279:Magnetic Resonance Imaging; D008297:Male; D009886:Ophthalmoplegia / Q000175:diagnosis / Q000209:etiology; D009915:Orbit / Q000098:blood supply*; D015911:Sclerotherapy / Q000009:adverse effects*; D012981:Sodium Tetradecyl Sulfate / Q000009:adverse effects*; D054079:Vascular Malformations / Q000000981:diagnostic imaging / Q000628:therapy*
D012981:Sodium Tetradecyl Sulfate
Eur Arch Otorhinolaryngol. 2016 Apr;273(4):1027-36
25731642
J Plast Reconstr Aesthet Surg. 2013 Feb;66(2):215-23
23059134
Int J Pediatr Otorhinolaryngol. 2012 Apr;76(4):569-73
22341629
Dermatol Surg. 2007 Oct;33(10):1250-4
17903159
Indian J Plast Surg. 2013 Jan;46(1):109-16
23960315
Phlebology. 2015 Jun;30(5):306-15
24827732
Scand J Plast Reconstr Surg Hand Surg. 1997 Jun;31(2):145-50
9232699
Ophthalmology. 1993 Apr;100(4):562-8
8479716