[About a case of laryngeal location of SAPHO].
BACKGROUND
Synovitis, acne, pustulosis, hyperostosis, osteitis (SAPHO) is a syndrome that combines dermatological, articular and osseous inflammatory manifestations. Bilateral laryngeal immobility relative to cricoarytenoid joint origin is very uncommon. This article presents a case of bilateral cricoarytenoid joint ankylosis in a SAPHO syndrome context.


METHODS
A 53-year-old patient presenting with a two year history of intermittent bouts of dyspnea. A SAPHO syndrome was discussed on repeated thoracic CT-scan. The link between dyspnea and SAPHO syndrome had not been made immediately given the absence of any known anteriority. However, having ruled out other etiologies and after having had to perform a tracheotomy due a worsening of the respiratory condition, this diagnosis was considered. Treatment by corticosteroids and infliximab permitted a clinical improvement of the patient.


CONCLUSIONS
This clinical case report should increase awareness of possible cricoarytenoid joint involvement in SAPHO.
Service d'ORL et chirurgie cervicofaciale, CHU La Conception, AP-HM, 147, boulevard Baille, 13005 Marseille, France. Electronic address: loraine.vatin@gmail.com.
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Vatin
Département de médecine interne, CHU La Timone, AP-HM, 13005 Marseille, France.
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Jean
Service d'ORL et chirurgie cervicofaciale, HIA Sainte-Anne, 83000 Toulon, France.
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Rivière
Service d'ORL et chirurgie cervicofaciale, CHU La Conception, AP-HM, 147, boulevard Baille, 13005 Marseille, France.
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Montava
Service d'ORL et chirurgie cervicofaciale, CHU La Conception, AP-HM, 147, boulevard Baille, 13005 Marseille, France.
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Giovanni
Service d'ORL et chirurgie cervicofaciale, CHU La Conception, AP-HM, 147, boulevard Baille, 13005 Marseille, France.
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Dessi
Service d'ORL et chirurgie cervicofaciale, CHU La Conception, AP-HM, 147, boulevard Baille, 13005 Marseille, France.
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Lagier
D020083:Acquired Hyperostosis Syndrome / Q000150:complications* / Q000175:diagnosis / Q000473:pathology; D004417:Dyspnea / Q000175:diagnosis / Q000209:etiology* / Q000473:pathology; D006801:Humans; D007818:Laryngeal Diseases / Q000175:diagnosis / Q000209:etiology* / Q000473:pathology; D007830:Larynx / Q000473:pathology*; D008297:Male; D008875:Middle Aged
Atteinte laryngée; Dyspnea; Dyspnée; Laryngeal involvement; SAPHO syndrome; Syndrome SAPHO